Anomalous origin of the left coronary artery from the pulmonary artery pulmonary artery trunk with myocardial ischemia and mitral with myocardial ischemia and mitral insufficiency

Authors

  • Ivana Vanesa Oliveri CEMIC University Institute. Buenos Aires. Argentina
  • Diego Xavier Chango-Azanza CEMIC University Institute. Buenos Aires. Argentina
  • Alejandro Deviggiano Department of Noninvasive Cardiovascular Studies. Maipú Diagnostics. Buenos Aires. Argentina
  • Martín Alejandro Munín CEMIC University Institute. Buenos Aires. Argentina
  • Gustavo Sánchez CEMIC University Institute. Buenos Aires. Argentina

DOI:

https://doi.org/10.37615/retic.v2n1a7

Keywords:

Bland-White- Garland Syndrome, anomalous origin of the left coronary artery from the trunk of the pulmonary artery (ALCAPA), myocardial ischemia, mitral regurgitation.

Abstract

We present the case of a patient with a diagnosis of anomalous origin of the left coronary artery from the trunk of the pulmonary artery (ALCAPA). The patient had a previous diagnosis of asymptomatic severe mitral regurgitation of unknown cause. The unexpected evidence of ischemia in the anterior and apical territory
in the stress echocardiogram requested for functional evaluation in addition to the characteristic echocardiographic signs suggested the presumptive diagnosis of ALCAPA, which was confirmed with non-invasive coronary CT.


Among the few patients with ALCAPA who reach adulthood, myocardial ischemia as initial presentation is rare

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References

Takaaki I, Hidekazu K, Yumi I, et al. A case of anomalous origin of the left coronary artery from the pulmonary artery presenting with sudden cardiac arrest due to coronary artery steal generated by excessive exercise. J Cardiol Cases 2016; 14: 145-148. doi: https://doi.org/10.1016/j.jccase.2016.07.001

Angelini P, Velasco JA, Flamm S. Coronary anomalies: incidence, pathophysiology, and clinical relevance. Circulation 2002; 105: 2449-2454. doi: https://doi.org/10.1161/01.cir.0000016175.49835.57

Pfannschmidt J, Ruskowski H, de Vivie E. Bland-White-Garland syndrome. Clinical aspects, diagnosis, therapy. Klin Padiatr 1992; 204: 328-334. doi: https://doi.org/10.1055/s-2007-1025367

Parizek P, Haman L, Harrer J, et al. Bland-White-Garland syndrome in adults: sudden cardiac death as a first symptom and long-term follow-up after successful resuscitation and surgery. Europace 2010; 12: 1338-1340. doi: https://doi.org/10.1093/europace/euq087

Safder T, Kvapil J, Vacek J, et al. Congenital coronary artery anomaly in an asymptomatic patient presenting with cardiac arrest. Kans J Med 2017;10: 1-8.

Khanna A, Torigian D, Ferrari V, et al. Anomalous origin of the left coronary artery from the pulmonary artery in adulthood on CT and MRI. Am J Roent-genol 2005; 185: 326-329. PMC5733454

Al Umairi RS, Al Kindi F, Al Busaidi F. Anomalous origin of the left coronary artery from the pulmonary artery: the role of multislice computed tomography (MSCT). Oman Med J 2016; 31: 387-389. doi: https://doi.org/10.5001/omj.2016.77.

Barbetakis N, Efstathiou A, Efstathiou N, et al. A long-term survivor of Bland-White-Garland syndrome with systemic collateral supply: A case report and review of the literature. BMC Surg 2005; 5: 23. doi: https://doi.org/10.1186/1471-2482-5-23

Published

2019-12-31

How to Cite

1.
Oliveri IV, Chango-Azanza DX, Deviggiano A, Alejandro Munín M, Sánchez G. Anomalous origin of the left coronary artery from the pulmonary artery pulmonary artery trunk with myocardial ischemia and mitral with myocardial ischemia and mitral insufficiency. Rev Ecocardiogr Pract Otras Tec Imag Card (RETIC) [Internet]. 2019 Dec. 31 [cited 2024 Nov. 24];2(1):26-9. Available from: https://imagenretic.org/RevEcocarPract/article/view/193