Anomalous origin of the left coronary artery from the pulmonary artery pulmonary artery trunk with myocardial ischemia and mitral with myocardial ischemia and mitral insufficiency
DOI:
https://doi.org/10.37615/retic.v2n1a7Keywords:
Bland-White- Garland Syndrome, anomalous origin of the left coronary artery from the trunk of the pulmonary artery (ALCAPA), myocardial ischemia, mitral regurgitation.Abstract
We present the case of a patient with a diagnosis of anomalous origin of the left coronary artery from the trunk of the pulmonary artery (ALCAPA). The patient had a previous diagnosis of asymptomatic severe mitral regurgitation of unknown cause. The unexpected evidence of ischemia in the anterior and apical territory
in the stress echocardiogram requested for functional evaluation in addition to the characteristic echocardiographic signs suggested the presumptive diagnosis of ALCAPA, which was confirmed with non-invasive coronary CT.
Among the few patients with ALCAPA who reach adulthood, myocardial ischemia as initial presentation is rare
Downloads
Metrics
References
Takaaki I, Hidekazu K, Yumi I, et al. A case of anomalous origin of the left coronary artery from the pulmonary artery presenting with sudden cardiac arrest due to coronary artery steal generated by excessive exercise. J Cardiol Cases 2016; 14: 145-148. doi: https://doi.org/10.1016/j.jccase.2016.07.001
Angelini P, Velasco JA, Flamm S. Coronary anomalies: incidence, pathophysiology, and clinical relevance. Circulation 2002; 105: 2449-2454. doi: https://doi.org/10.1161/01.cir.0000016175.49835.57
Pfannschmidt J, Ruskowski H, de Vivie E. Bland-White-Garland syndrome. Clinical aspects, diagnosis, therapy. Klin Padiatr 1992; 204: 328-334. doi: https://doi.org/10.1055/s-2007-1025367
Parizek P, Haman L, Harrer J, et al. Bland-White-Garland syndrome in adults: sudden cardiac death as a first symptom and long-term follow-up after successful resuscitation and surgery. Europace 2010; 12: 1338-1340. doi: https://doi.org/10.1093/europace/euq087
Safder T, Kvapil J, Vacek J, et al. Congenital coronary artery anomaly in an asymptomatic patient presenting with cardiac arrest. Kans J Med 2017;10: 1-8.
Khanna A, Torigian D, Ferrari V, et al. Anomalous origin of the left coronary artery from the pulmonary artery in adulthood on CT and MRI. Am J Roent-genol 2005; 185: 326-329. PMC5733454
Al Umairi RS, Al Kindi F, Al Busaidi F. Anomalous origin of the left coronary artery from the pulmonary artery: the role of multislice computed tomography (MSCT). Oman Med J 2016; 31: 387-389. doi: https://doi.org/10.5001/omj.2016.77.
Barbetakis N, Efstathiou A, Efstathiou N, et al. A long-term survivor of Bland-White-Garland syndrome with systemic collateral supply: A case report and review of the literature. BMC Surg 2005; 5: 23. doi: https://doi.org/10.1186/1471-2482-5-23
Downloads
Published
How to Cite
Issue
Section
License
Copyright (c) 2019 Ivana Vanesa Oliveri, Diego Xavier Chango-Azanza, Alejandro Deviggiano, Martín Alejandro Munín, Gustavo Sánchez
This work is licensed under a Creative Commons Attribution-NonCommercial-NoDerivatives 4.0 International License.
RETIC is distributed under the Creative Commons Attribution-NonCommercial-NoDerivatives 4.0 International (CC BY-NC-ND 4.0) license https://creativecommons.org/licenses/by-nc-nd/4.0 which allows sharing, copying and redistribution of the material in any medium or format, under the following terms:
- Attribution: you must give appropriate credit, provide a link to the license, and indicate if changes were made. You may do so in any reasonable manner, but not in any way that suggests that the licensor endorses you or your use.
- Non-commercial: you may not use the material for commercial purposes.
- No Derivatives: if you remix, transform or build upon the material, you may not distribute the modified material.
- No Additional Restrictions: you may not apply legal terms or technological measures that legally restrict others from doing anything permitted by the license.